학술논문

Transcriptome-wide isoform-level dysregulation in ASD, schizophrenia, and bipolar disorder
Document Type
article
Author
Gandal, Michael JZhang, PanHadjimichael, EviWalker, Rebecca LChen, ChaoLiu, ShuangWon, Hyejungvan Bakel, HarmVarghese, MerinaWang, YongjunShieh, Annie WHaney, JillianParhami, SepidehBelmont, JudsonKim, MinsooMoran Losada, PatriciaKhan, ZenabMleczko, JustynaXia, YanDai, RujiaWang, DaifengYang, Yucheng TXu, MinFish, KennethHof, Patrick RWarrell, JonathanFitzgerald, DominicWhite, KevinJaffe, Andrew EPeters, Mette AGerstein, MarkLiu, ChunyuIakoucheva, Lilia MPinto, DalilaGeschwind, Daniel HAshley-Koch, Allison ECrawford, Gregory EGarrett, Melanie ESong, LingyunSafi, AlexiasJohnson, Graham DWray, Gregory AReddy, Timothy EGoes, Fernando SZandi, PeterBryois, JulienPrice, Amanda JIvanov, Nikolay ACollado-Torres, LeonardoHyde, Thomas MBurke, Emily EKleiman, Joel ETao, RanShin, Joo HeonAkbarian, SchahramGirdhar, KiranJiang, YanKundakovic, MarijaBrown, LeanneKassim, Bibi SPark, Royce BWiseman, Jennifer RZharovsky, ElizabethJacobov, RivkaDevillers, OliviaFlatow, ElieHoffman, Gabriel ELipska, Barbara KLewis, David AHaroutunian, VahramHahn, Chang-GyuCharney, Alexander WDracheva, StellaKozlenkov, AlexeyDelValle, DianeFrancoeur, NancyRoussos, PanosFullard, John FBendl, JaroslavHauberg, Mads EMangravite, Lara MChae, YooreePeng, JunminNiu, MingmingWang, XushengWebster, Maree JBeach, Thomas GJiang, YiGrennan, Kay S
Source
Science. 362(6420)
Subject
Pharmacology and Pharmaceutical Sciences
Biological Sciences
Biomedical and Clinical Sciences
Genetics
Autism
Mental Health
Intellectual and Developmental Disabilities (IDD)
Brain Disorders
Neurosciences
Human Genome
Bipolar Disorder
Schizophrenia
Serious Mental Illness
Biotechnology
2.1 Biological and endogenous factors
Aetiology
Mental health
Good Health and Well Being
Autism Spectrum Disorder
Brain
Genetic Predisposition to Disease
Humans
Protein Isoforms
RNA Splicing
Sequence Analysis
RNA
Transcriptome
PsychENCODE Consortium
General Science & Technology
Language
Abstract
Most genetic risk for psychiatric disease lies in regulatory regions, implicating pathogenic dysregulation of gene expression and splicing. However, comprehensive assessments of transcriptomic organization in diseased brains are limited. In this work, we integrated genotypes and RNA sequencing in brain samples from 1695 individuals with autism spectrum disorder (ASD), schizophrenia, and bipolar disorder, as well as controls. More than 25% of the transcriptome exhibits differential splicing or expression, with isoform-level changes capturing the largest disease effects and genetic enrichments. Coexpression networks isolate disease-specific neuronal alterations, as well as microglial, astrocyte, and interferon-response modules defining previously unidentified neural-immune mechanisms. We integrated genetic and genomic data to perform a transcriptome-wide association study, prioritizing disease loci likely mediated by cis effects on brain expression. This transcriptome-wide characterization of the molecular pathology across three major psychiatric disorders provides a comprehensive resource for mechanistic insight and therapeutic development.