학술논문

Mutations in XPR1 cause primary familial brain calcification associated with altered phosphate export.
Document Type
article
Source
Nature genetics. 47(6)
Subject
Humans
Brain Diseases
Metabolic
Inborn
Neurodegenerative Diseases
Calcinosis
Genetic Predisposition to Disease
Receptors
G-Protein-Coupled
Receptors
Virus
Pedigree
DNA Mutational Analysis
Lod Score
Mutation
Missense
Middle Aged
Female
Male
Genetic Association Studies
HEK293 Cells
Xenotropic and Polytropic Retrovirus Receptor
Neurosciences
Rare Diseases
2.1 Biological and endogenous factors
Aetiology
Biological Sciences
Medical and Health Sciences
Developmental Biology
Language
Abstract
Primary familial brain calcification (PFBC) is a neurological disease characterized by calcium phosphate deposits in the basal ganglia and other brain regions and has thus far been associated with SLC20A2, PDGFB or PDGFRB mutations. We identified in multiple families with PFBC mutations in XPR1, a gene encoding a retroviral receptor with phosphate export function. These mutations alter phosphate export, implicating XPR1 and phosphate homeostasis in PFBC.